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DOI: 10.1055/a-2641-6301
Extremely Rare Presentation of Pilonidal Sinus Disease in the Posterior Cranial Fossa of a 2-Year-Old Patient: A Case Report

Abstract
A 2-year-old female patient presented after experiencing a generalized tonic-clonic seizure accompanied by fever, followed by a loss of consciousness. She underwent an urgent right frontal external ventricular drain placement. Intraoperative cerebrospinal fluid analysis was negative for infectious patterns. MRI showed a predominantly cystic lesion in the midline posterior fossa, with a compressive mass effect. Subsequently, she underwent a suboccipital craniotomy for microscopic resection of a posterior cranial fossa lesion. Histopathology reported keratin flakes with severe active inflammation, and foreign body type giant cell reaction in scalp excision with free hair shafts through the inflammatory focus, consistent with pilonidal sinus. The patient was then discharged home in good health.
Ethical Approval
Our institution does not require ethical approval for reporting individual cases or case series.
Informed Consent
Written informed consent was obtained from a legally authorized representative(s) for anonymized patient information to be published in this article.
Publication History
Received: 27 December 2024
Accepted: 22 June 2025
Article published online:
11 July 2025
© 2025. The Author(s). This is an open access article published by Thieme under the terms of the Creative Commons Attribution License, permitting unrestricted use, distribution, and reproduction so long as the original work is properly cited. (https://creativecommons.org/licenses/by/4.0/)
Georg Thieme Verlag KG
Oswald-Hesse-Straße 50, 70469 Stuttgart, Germany
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References
- 1 Hodges RM. Pilo-Nidal Sinus. Boston Med Surg J 1880; 103 (21) 485-486
- 2 Sion-Vardy N, Osyntsov L, Cagnano E, Osyntsov A, Vardy D, Benharroch D. Unexpected location of pilonidal sinuses. Clin Exp Dermatol 2009; 34 (08) e599-e601
- 3 Rao AR, Sharma M, Thyveetil M, Karim OMA. Penis: an unusual site for pilonidal sinus. Int Urol Nephrol 2006; 38 (3–4): 607-608
- 4 de Parades V, Bouchard D, Janier M, Berger A. Pilonidal sinus disease. J Visc Surg 2013; 150 (04) 237-247
- 5 Shinde P, Toshikhane H. Pilonidal sinus (Nadi vrana): a case study. Int J Ayurveda Res 2010; 1 (03) 181-182
- 6 Borges G, Maciel Júnior JA, Carelli EF, Alvarenga M, De Castro R, Bonilha L. Pilonidal cyst on the vault. Case report. Arq Neuropsiquiatr 1999; 57 (2A): 273-276
- 7 Nixon AT, Garza RF. Pilonidal Cyst and Sinus. StatPearls. Published online August 8, 2023. Accessed April 8, 2025 at: https://www.ncbi.nlm.nih.gov/books/NBK557770/
- 8 Adhikari BN, Khatiwada S, Bhattarai A. Pilonidal sinus of the cheek: an extremely rare clinical entity-case report and brief review of the literature. J Med Case Rep 2021; 15 (01) 64
- 9 Salih AM, Ahmed RS, Zahir HM. et al. Axillary pilonidal sinus: an unusual presentation: a case report with literature review. Oxf Med Case Rep 2024; 2024 (10) omae123
- 10 Shanmugathas N, Yassin M, Ross C, Minhas S. Pilonidal sinus disease of the penis: a case report and review of the literature. Andrologia 2021; 53 (01) e13837
- 11 O'Kane HF, Duggan B, Mulholland C, Crosbie J. Pilonidal sinus of the penis. Sci World J 2004; 4 (Suppl. 01) 258-259
- 12 Chikkamuniyappa S, Scott RS, Furman J. Pilonidal sinus of the glans penis associated with actinomyces case reports and review of literature. Sci World J 2004; 4: 908-912
- 13 Akkapulu N, Akkapulu N, Tanrikulu Y. Umbilical pilonidal sinus: a case report. J Med Cases 2011; 2 (06) 272-274
- 14 Ngan PG, Varey AHR, Mahajan AL. Periungual pilonidal sinus. J Hand Surg Eur Vol 2011; 36 (02) 155-157
- 15 Çiftci F, Abdurrahman I. A different disease: extrasacrococcygeal pilonidal sinuses etiopathogenesis. Int J Clin Exp Med 2015; 8 (07) 11567-11571
- 16 Pilonidal P, Bir N, Sunumu O, Derlemesi KL, Yılmaz GO, Yılmaz G. Postauricular pilonidal sinus: a rare case report and brief literature review postauricular pilonidal sinus: a rare case report and brief literature review. Osmangazi Tıp Dergisi Osmangazi J Med 2023; 2023 (04) 605-609
- 17 Destek S, Gul VO, Ahioglu S. Rare type cranial postauricular pilonidal sinus: a case report and brief review of literature. Case Rep Surg 2017; 2017: 5791972
- 18 Shareef SH, Hawrami TA, Salih AM. et al. Intermammary pilonidal sinus: the first case series. Int J Surg Case Rep 2017; 41: 265-268
- 19 Wilson E, Failes DG, Killingback M. Pilonidal sinuses of the anal canal: report of a case. Dis Colon Rectum 1971; 14 (06) 468-470
- 20 Baviskar RH, Baviskar RR, Wagh KD. Pilonidal sinus of the anal canal: a rare entity – case report. J Coloproctol (Rio J) 2024; 44 (01) e71-e74
- 21 Nagra I, Wee B, Short J, Banerjee AK. The role of cranial CT in the investigation of meningitis. JRSM Short Rep 2011; 2 (03) 20
- 22 Sumer MM, Açikgöz B, Akpinar G. External ventricular drainage for acute obstructive hydrocephalus developing following spontaneous intracerebral haemorrhages. Neurol Sci 2002; 23 (01) 29-33
- 23 Knight J, Karsonovich T, De Jesus O. Pilocytic Astrocytoma. StatPearls. Published online August 7, 2024. Accessed April 8, 2025 at: https://www.ncbi.nlm.nih.gov/books/NBK560614/