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CC BY 4.0 · European J Pediatr Surg Rep. 2023; 11(01): e5-e9
DOI: 10.1055/a-2021-8054
Case Report

Endobronchial Inflammatory Myofibroblastic Tumor in a 3-Year-Old Child

Riccardo Guanà   *
1   Division of Pediatric General, Thoracic & Minimally Invasive Surgery, University Hospital of Health and Science, Turin University, Regina Margherita Children's Hospital, Torino, Italy
,
Andrea Carpino   *
1   Division of Pediatric General, Thoracic & Minimally Invasive Surgery, University Hospital of Health and Science, Turin University, Regina Margherita Children's Hospital, Torino, Italy
,
Marta Miglietta
1   Division of Pediatric General, Thoracic & Minimally Invasive Surgery, University Hospital of Health and Science, Turin University, Regina Margherita Children's Hospital, Torino, Italy
,
Elisa Zambaiti 
1   Division of Pediatric General, Thoracic & Minimally Invasive Surgery, University Hospital of Health and Science, Turin University, Regina Margherita Children's Hospital, Torino, Italy
,
Alessia Cerrina
1   Division of Pediatric General, Thoracic & Minimally Invasive Surgery, University Hospital of Health and Science, Turin University, Regina Margherita Children's Hospital, Torino, Italy
,
Luca Lonati
1   Division of Pediatric General, Thoracic & Minimally Invasive Surgery, University Hospital of Health and Science, Turin University, Regina Margherita Children's Hospital, Torino, Italy
,
Francesco Guerrera
1   Division of Pediatric General, Thoracic & Minimally Invasive Surgery, University Hospital of Health and Science, Turin University, Regina Margherita Children's Hospital, Torino, Italy
,
Stefano Vallero
1   Division of Pediatric General, Thoracic & Minimally Invasive Surgery, University Hospital of Health and Science, Turin University, Regina Margherita Children's Hospital, Torino, Italy
,
Salvatore Garofalo
1   Division of Pediatric General, Thoracic & Minimally Invasive Surgery, University Hospital of Health and Science, Turin University, Regina Margherita Children's Hospital, Torino, Italy
,
Marco Bardessono
1   Division of Pediatric General, Thoracic & Minimally Invasive Surgery, University Hospital of Health and Science, Turin University, Regina Margherita Children's Hospital, Torino, Italy
,
Francesca Maletta
1   Division of Pediatric General, Thoracic & Minimally Invasive Surgery, University Hospital of Health and Science, Turin University, Regina Margherita Children's Hospital, Torino, Italy
,
Steffi Shilly
2   Columbia University School of Nursing, New York, New York, United States
,
Fabrizio Gennari
1   Division of Pediatric General, Thoracic & Minimally Invasive Surgery, University Hospital of Health and Science, Turin University, Regina Margherita Children's Hospital, Torino, Italy
› Institutsangaben Funding No grant was received for this study.
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Abstract

Inflammatory myofibroblastic tumor (IMT) is a mesenchymal tumor that can occur at any age. However, it is primarily seen in children, with the most common site being in the lung parenchyma, usually present with rare endobronchial lesions. This case reports the incidence in a 3-year-old girl diagnosed with pericardiac pneumonia treated with antibiotics with no clinical improvement. A chest computed tomography (CT) scan identified a 1.5-cm lesion in the left main bronchus. Bronchoscopy revealed complete obstruction of the left main stem bronchus. A left posterolateral thoracotomy was performed. Additionally, a left sleeve upper bronchial resection was conducted under fibroendoscopic control. Definitive histology confirmed IMT. After 2 years of endoscopic follow-up, there is no evidence of recurrence.

Keywords

myofibroblastic tumor - bronchoscopy - thoracotomy

Ethical Approval

All procedures performed in this study were in accordance with the ethical standards of the Institutional and National Research Committee and with the 1964 Helsinki Declaration and its later amendments or comparable ethical standards.


Informed consent was obtained from all individual participants (children's parents) included in the study.


The manuscript has been read and approved by all the authors; the requirements for authorship have been met and each author believes that the manuscript represents honest work.


The manuscript has not been sent elsewhere during this submission.


* Both authors equally contributed to the work.




Publikationsverlauf

Eingereicht: 03. Juni 2022

Angenommen: 13. Dezember 2022

Accepted Manuscript online:
28. Januar 2023

Artikel online veröffentlicht:
16. März 2023

© 2023. The Author(s). This is an open access article published by Thieme under the terms of the Creative Commons Attribution License, permitting unrestricted use, distribution, and reproduction so long as the original work is properly cited. (https://creativecommons.org/licenses/by/4.0/)

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